Adult-onset MLD: a gene mutation with isolated polyneuropathy.

Felice, K J; Gomez Lira, M; Natowicz, M; Grunnet, M L; Tsongalis, G J; Sima, A A; Kaplan, R F · Neurology · 2000

case_report · Level V

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Abstract

A 22-year-old man presented with recurrent ulnar mononeuropathies and diffusely slow nerve conduction velocities. Arylsulfatase A (ASA) activity from leukocytes and fibroblasts was reduced, and urinary sulfatides were increased. Sural nerve biopsy revealed a reduction in myelinated fibers and Schwann cell inclusions. Results of studies of CNS integrity, including cranial MRI, evoked potentials, and neuropsychologic tests, were normal. Molecular genetic analyses revealed a novel homozygous missense mutation (Thr286Pro) in the ASA gene.

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