Mutations in two nonhomologous genes in a head-to-head configuration cause Ellis-van Creveld syndrome.

Ruiz-Perez, Victor L; Tompson, Stuart W J; Blair, Helen J; Espinoza-Valdez, Cecilia; Lapunzina, Pablo; Silva, Elias O; Hamel, Ben; Gibbs, John L et al. · Am J Hum Genet · 2003

basic_science · Level V

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Abstract

Ellis-van Creveld syndrome (EvC) is an autosomal recessive skeletal dysplasia. Elsewhere, we described mutations in EVC in patients with this condition (Ruiz-Perez et al. 2000). We now report that mutations in EVC2 also cause EvC. These two genes lie in a head-to-head configuration that is conserved from fish to man. Affected individuals with mutations in EVC and EVC2 have the typical spectrum of features and are phenotypically indistinguishable.

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