Evidence for genetic heterogeneity in lymphedema-cholestasis syndrome.

Frühwirth, Martin; Janecke, Andreas R; Müller, Thomas; Carlton, Victoria E H; Kronenberg, Florian; Offner, Felix; Knisely, A S; Geleff, Silvana et al. · J Pediatr · 2003

case_report · Level V

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Abstract

Lymphedema-cholestasis syndrome (LCS, Aagenaes syndrome) is the only known form of hereditary lymphedema associated with cholestasis. A locus, LCS1, has recently been mapped to chromosome 15q in a Norwegian kindred. In a consanguine Serbian Romani family with a neonate who had a combination of lymphedema and cholestasis with features atypical for Norwegian LCS, haplotype and linkage analysis of markers spanning the LCS1 region argue that a second LCS locus may exist. The infant may represent an instance of a previously undescribed lymphedema-cholestasis syndrome.

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