Novel prion protein gene mutation presenting with subacute PSP-like syndrome.

Rowe, D B; Lewis, V; Needham, M; Rodriguez, M; Boyd, A; McLean, C; Roberts, H; Masters, C L et al. · Neurology · 2007

case_report · Level V

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Abstract

A 62-year-old Indonesian woman presenting with a progressive supranuclear palsy-like syndrome was confirmed post mortem as dying from a spongiform encephalopathy. Despite an illness duration of only 4 months, brain MRI, EEG, and CSF analysis for 14-3-3 proteins all failed to disclose changes typical of Creutzfeldt-Jakob disease. Neuropathologic examination revealed multicentric, prion protein-positive, amyloid plaques as typically seen in Gerstmann-Sträussler-Scheinker syndrome. Prion protein gene analysis revealed a previously unreported A133V mutation.

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