Delayed Presentation and Prolonged Survival of a Child with Surfactant Protein B Deficiency.

López-Andreu, Juan A; Hidalgo-Santos, Antonio D; Fuentes-Castelló, Miguel A; Mancheño-Franch, Nuria; Cerón-Pérez, Juan A; Esteban-Ricós, Maria J; Pedrola-Vidal, Laia; Nogee, Lawrence M · J Pediatr · 2017

case_report · Level V

Where this comes from

Abstract

Surfactant protein B encoding gene mutations have been related to early onset fatal respiratory distress in full-term neonates. We report a school-aged male child homozygous for a surfactant protein B encoding gene missense mutation who presented after the neonatal period. His respiratory insufficiency responded to high dose intravenous methylprednisolone and hydroxychloroquine.

Medical subject headings