Genome Sequencing Identifies the Pathogenic Variant Missed by Prior Testing in an Infant with Marfan Syndrome.

Wojcik, Monica H; Thiele, Katri; Grant, Carly F; Chao, Katherine; Goodrich, Julia; O'Donnell-Luria, Anne; Lacro, Ronald V; Tan, Wen-Hann et al. · J Pediatr · 2019

case_report · Level V

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Abstract

We describe an infant with a phenotype typical of early onset Marfan syndrome whose genetic evaluation, including Sanger sequencing and deletion/duplication testing of FBN1 and exome sequencing, was negative. Ultimately, genome sequencing revealed a deletion missed on prior testing, demonstrating the unique utility of genome sequencing for molecular genetic diagnosis.

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