From Dysgammaglobulinemia to Autosomal-Dominant Activation-Induced Cytidine Deaminase Deficiency: Unraveling an Inherited Immunodeficiency after 50 Years.

Fadlallah, Jehane; Chentout, Loic; Boisson, Bertrand; Pouliet, Aurore; Masson, Cecile; Morin, Florence; Durandy, Anne; Casanova, Jean-Laurent et al. · J Pediatr · 2020

case_report · Level V

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Abstract

The genetic investigation of a family presenting with a dominant form of hyper IgM syndrome published in 1963 and 1975 revealed a R190X nonsense mutation in activation-induced cytidine deaminase. This report illustrates the progress made over 6 decades in the characterization of primary immunodeficiencies, from immunochemistry to whole-exome sequencing.

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